Recurrence of a primary xanthoma of the humerus in a 9-year-old normolipidemic child

• Published in: Archives de pédiatrie : organe officiel de la Société française de pédiatrie Vol. 26; no. 7; pp. 411 - 414
• Main Authors: David, E., Dupont, C., Desdoits, A., Bronfen, C., Laquievre, A.
• Format: Journal Article
• Language: English
• Published: France Elsevier Masson SAS 01-10-2019; Elsevier
• Subjects: Bone Diseases - diagnosis; Bone Diseases - pathology; Bone Diseases - surgery; Child; Humans; Humerus - pathology; Humerus - surgery; Hyperlipidemia; Hyperlipidemias; Life Sciences; Male; Pathologic fracture; Primary intraosseous xanthoma; Recurrence; Xanthomatosis - diagnosis; Xanthomatosis - pathology; Xanthomatosis - surgery; Hyperlipidemia; Pathologic fracture; Primary intraosseous xanthoma
• ISSN: 0929-693X; 1769-664X
• DOI: 10.1016/j.arcped.2019.09.010

Xanthomas are rare bone tumors that occur more often in patients with hyperlipidemia or metabolic disorders. We report the case of a 9-year-old child presenting with right shoulder pain after a trauma. A benign osteolytic lesion was found in the proximal humeral metaphysis. Curettage of the lesion was performed. Histologic findings confirmed intraosseous xanthoma. Although there was no evidence of dyslipidemia or metabolic disease, the patient suffered local recurrence at the 8-month follow-up, requiring a second surgery with bone grafting. This difficult and rare diagnosis must be kept in mind with osteolytic lesions.